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Hongzheng Dai

Baylor Genetics · US
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Area of research
Genetics · Clinical Biochemistry
Research interest
Research interests include Genomics and Rare Diseases, Genomic variations and chromosomal abnormalities, Genetics and Neurodevelopmental Disorders, and Metabolism and Genetic Disorders.
h-index
31
citations
3,465
works
151
NIH funding
primary concept
email

Recent publications

Biallelic LAMP3 variants in 5 families with interstitial lung disease: Evidence of a disease-gene association
Genetics in Medicine 2026cited by 3position: middledoi
Joint, multifaceted genomic analysis enables diagnosis of diverse, ultra-rare monogenic presentations
Nature Communications 2025cited by 3position: middledoi
Large-scale mutational analysis identifies UNC93B1 variants that drive TLR-mediated autoimmunity in mice and humans
The Journal of Experimental Medicine 2024cited by 34position: middledoi
Diagnostic utility of DNA methylation analysis in genetically unsolved pediatric epilepsies and CHD2 episignature refinement
Nature Communications 2024cited by 21position: middledoi
Bi-allelic variants in INTS11 are associated with a complex neurological disorder
The American Journal of Human Genetics 2023cited by 36position: middledoi
<i>SPTSSA</i> variants alter sphingolipid synthesis and cause a complex hereditary spastic paraplegia
Brain 2023cited by 34position: middledoi
Evaluation of an automated genome interpretation model for rare disease routinely used in a clinical genetic laboratory
Genetics in Medicine 2023cited by 32position: middledoi
Bi-allelic ATG4D variants are associated with a neurodevelopmental disorder characterized by speech and motor impairment
npj Genomic Medicine 2023cited by 18position: middledoi
The Rare and Atypical Diabetes Network (RADIANT) Study: Design and Early Results
Diabetes Care 2023cited by 15position: middledoi
The microRNA processor<i>DROSHA</i>is a candidate gene for a severe progressive neurological disorder
Human Molecular Genetics 2022cited by 17position: middledoi
Endocannabinoid dysfunction in neurological disease: neuro-ocular DAGLA-related syndrome
Brain 2022cited by 15position: middledoi
Phenotypic expansion of CACNA1C-associated disorders to include isolated neurological manifestations
Genetics in Medicine 2021cited by 49position: middledoi
Commonalities across computational workflows for uncovering explanatory variants in undiagnosed cases
Genetics in Medicine 2021cited by 34position: middledoi
Variants in PRKAR1B cause a neurodevelopmental disorder with autism spectrum disorder, apraxia, and insensitivity to pain
Genetics in Medicine 2021cited by 27position: middledoi
Heterozygous loss-of-function variants significantly expand the phenotypes associated with loss of GDF11
Genetics in Medicine 2021cited by 26position: middledoi
<scp> <i>PPP3CA</i> </scp> truncating variants clustered in the regulatory domain cause early‐onset refractory epilepsy
Clinical Genetics 2021cited by 25position: middledoi
Transcriptome-directed analysis for Mendelian disease diagnosis overcomes limitations of conventional genomic testing
Journal of Clinical Investigation 2020cited by 184position: middledoi
Dominant-negative mutations in human <i>IL6ST</i> underlie hyper-IgE syndrome
The Journal of Experimental Medicine 2020cited by 112position: middledoi
De novo EIF2AK1 and EIF2AK2 Variants Are Associated with Developmental Delay, Leukoencephalopathy, and Neurologic Decompensation
The American Journal of Human Genetics 2020cited by 69position: middledoi
An autosomal dominant neurological disorder caused by de novo variants in FAR1 resulting in uncontrolled synthesis of ether lipids
Genetics in Medicine 2020cited by 49position: middledoi
BICRA, a SWI/SNF Complex Member, Is Associated with BAF-Disorder Related Phenotypes in Humans and Model Organisms
The American Journal of Human Genetics 2020cited by 48position: middledoi
Clinical sites of the Undiagnosed Diseases Network: unique contributions to genomic medicine and science
Genetics in Medicine 2020cited by 42position: middledoi
Reanalysis of Clinical Exome Sequencing Data
New England Journal of Medicine 2019cited by 296position: middledoi
Non-invasive prenatal sequencing for multiple Mendelian monogenic disorders using circulating cell-free fetal DNA
Nature Medicine 2019cited by 261position: middledoi
Clinical exome sequencing for fetuses with ultrasound abnormalities and a suspected Mendelian disorder
Genome Medicine 2018cited by 161position: middledoi
Use of Exome Sequencing for Infants in Intensive Care Units
JAMA Pediatrics 2017cited by 429position: middledoi
<i>MPV17</i>-related mitochondrial DNA maintenance defect: New cases and review of clinical, biochemical, and molecular aspects
Human Mutation 2017cited by 64position: middledoi

Grants

No grants ingested yet.

Frequent collaborators

Rui Xiao · Wuhan University3 papers (2018–2023)Christine M. Eng · Baylor Genetics3 papers (2018–2023)Fan Xia · Baylor Genetics3 papers (2018–2023)Pengfei Liu · Macau University of Science and Technology2 papers (2018–2020)Linyan Meng · Baylor College of Medicine2 papers (2018–2023)Jill A. Rosenfeld · Baylor College of Medicine2 papers (2020–2021)Julia Wang · University of Minnesota2 papers (2017–2021)Pankaj Prasun · Professional Beef Services1 papers (2017–2017)Avinash V. Dharmadhikari · Children's Hospital of Los Angeles1 papers (2018–2018)Tomer Talmy · Hebrew University of Jerusalem1 papers (2023–2023)Saadet Mercimek‐Andrews · Hospital for Sick Children1 papers (2021–2021)Weimin Bi · Baylor College of Medicine1 papers (2018–2018)Shan Chen · Jiangsu Academy of Agricultural Sciences1 papers (2020–2020)Xia Wang · Union Hospital1 papers (2018–2018)Yaping Yang · Ningbo University1 papers (2018–2018)Henry C. Lin · Louisiana State University Health Sciences Center New Orleans1 papers (2017–2017)Paolo Moretti · Sanford Health1 papers (2020–2020) · 1 papers (2023–2023)Chunjing Qu · Union Hospital1 papers (2018–2018)Ruben Attali · Hebrew University of Jerusalem1 papers (2023–2023)
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