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Silvia De Rubeis

Allen Institute for Brain Science · US
Area of research
Genetics · Cognitive Neuroscience
Research interest
Research interests include Genetics and Neurodevelopmental Disorders, Autism Spectrum Disorder Research, Genomics and Rare Diseases, and Congenital heart defects research.
h-index
41
citations
17,834
works
135
NIH funding
primary concept
Biology
email

Recent publications

Examining Genetic Variants Associated with FOXP1 Syndrome through Molecular Dynamics of Its DNA-Binding Domain and Self-Organizing Maps
Journal of Chemical Information and Modeling 2026cited by 1position: middledoi
Deleterious coding variation associated with autism is shared across ancestries
Nature Medicine 2026cited by 0position: middledoi
Sex-specific perturbations of neuronal development caused by mutations in the autism risk gene DDX3X
Nature Communications 2025cited by 8position: lastdoi
A subpopulation of cortical neurons altered by mutations in the autism risk gene <i>DDX3X</i>
Biology Open 2025cited by 3position: lastdoi
Deleterious coding variation associated with autism is consistent across populations, as exemplified by admixed Latin American populations
medRxiv 2025cited by 3position: middledoi
Impact of Genetic Variants Associated with Neurodevelopmental Disorders on the WAVE Regulatory Complex
Journal of Chemical Information and Modeling 2025cited by 1position: middledoi
Expanding the understanding of DDX3X-related neurodevelopmental disorder in males
European Journal of Human Genetics 2025cited by 0position: firstdoi
Common characteristics of variants linked to autism spectrum disorder in the WAVE regulatory complex
Frontiers in Computational Neuroscience 2025cited by 0position: middledoi
Neuronal diversity and stereotypy at multiple scales through whole brain morphometry
Nature Communications 2024cited by 16position: middledoi
<scp>DDX3X</scp> syndrome: From clinical phenotypes to biological insights
Journal of Neurochemistry 2024cited by 12position: lastdoi
Molecular basis of the <scp>CYFIP2</scp> and <scp>NCKAP1</scp> autism‐linked variants in the <scp>WAVE</scp> regulatory complex
Protein Science 2024cited by 4position: middledoi
Sex-specific perturbations of neuronal development caused by mutations in the autism risk gene <i>DDX3X</i>
bioRxiv (Cold Spring Harbor Laboratory) 2024cited by 4position: lastdoi
Skipping of Exon 20 in <i>EP300</i> : A Novel Variant Linked to Rubinstein–Taybi Syndrome With Atypical and Severe Clinical Manifestations
Clinical Genetics 2024cited by 1position: middledoi
Celf4 controls mRNA translation underlying synaptic development in the prenatal mammalian neocortex
Nature Communications 2023cited by 35position: middledoi
Altered striatal actin dynamics drives behavioral inflexibility in a mouse model of fragile X syndrome
Neuron 2023cited by 34position: middledoi
The clinical and molecular spectrum of the KDM6B-related neurodevelopmental disorder
The American Journal of Human Genetics 2023cited by 30position: middledoi
Skewed X-chromosome inactivation in unsolved neurodevelopmental disease cases can guide re-evaluation For X-linked genes
European Journal of Human Genetics 2023cited by 23position: middledoi
Nuclear RNA catabolism controls endogenous retroviruses, gene expression asymmetry, and dedifferentiation
Molecular Cell 2023cited by 19position: middledoi
Missense variants in RPH3A cause defects in excitatory synaptic function and are associated with a clinically variable neurodevelopmental disorder
Genetics in Medicine 2023cited by 16position: middledoi
Full-Spectrum Neuronal Diversity and Stereotypy through Whole Brain Morphometry
Research Square 2023cited by 10position: middledoi
Modelling eNvironment for Isoforms (MoNvIso): A general platform to predict structural determinants of protein isoforms in genetic diseases
Frontiers in Chemistry 2023cited by 1position: middledoi
Clonally expanded CD8 T cells characterize amyotrophic lateral sclerosis-4
Nature 2022cited by 87position: middledoi
<i>CAPRIN1</i> haploinsufficiency causes a neurodevelopmental disorder with language impairment, ADHD and ASD
Brain 2022cited by 37position: middledoi
Author Correction: Clonally expanded CD8 T cells characterize amyotrophic lateral sclerosis-4
Nature 2022cited by 1position: middledoi
Modelling eNvironment for Isoforms (MoNvIso): A general platform to predict structural determinants of protein isoforms in genetic diseases
bioRxiv (Cold Spring Harbor Laboratory) 2022cited by 0position: middledoi
How rare and common risk variation jointly affect liability for autism spectrum disorder
Molecular Autism 2021cited by 65position: middledoi
Prospective and detailed behavioral phenotyping in DDX3X syndrome
Molecular Autism 2021cited by 61position: middledoi
Prevalence and phenotypic impact of rare potentially damaging variants in autism spectrum disorder
Molecular Autism 2021cited by 41position: middledoi
Developmental and Behavioral Phenotypes in a Mouse Model of DDX3X Syndrome
Biological Psychiatry 2021cited by 41position: lastdoi
Rare coding variation illuminates the allelic architecture, risk genes, cellular expression patterns, and phenotypic context of autism
medRxiv 2021cited by 35position: middledoi

Grants

No grants ingested yet.

Frequent collaborators

Joseph D. Buxbaum · Child Health and Development Institute27 papers (2013–2024)Marta García-Forn · Biomedical Research Networking Center on Neurodegenerative Diseases9 papers (2020–2025)Dorothy E. Grice · Mount Sinai Hospital7 papers (2018–2021)Hala Harony‐Nicolas · Allen Institute for Brain Science5 papers (2013–2019)Alexander Kolevzon · Boston Children's Hospital5 papers (2015–2021)Paolo Carloni · Forschungszentrum Jülich5 papers (2022–2025) · 5 papers (2022–2025)Claudia Bagni · University of Lausanne4 papers (2012–2023)Yeaji Park · Allen Institute for Brain Science4 papers (2021–2025)Danielle Halpern · University of Illinois Chicago4 papers (2018–2021)Daniele Di Marino · KU Leuven4 papers (2012–2019)Bernie Devlin · University of Pittsburgh4 papers (2013–2021)Michael S. Breen · Beijing Obstetrics and Gynecology Hospital4 papers (2018–2021)Elodie Drapeau · Icahn School of Medicine at Mount Sinai4 papers (2013–2021)Paige M. Siper · University of Bristol4 papers (2018–2021)Alfredo Brusco · CTO Hospital4 papers (2017–2024)Kristi Niblo · Allen Institute for Brain Science4 papers (2018–2021)Andrea Boitnott · Allen Institute for Brain Science4 papers (2020–2025)Kathryn Roeder · University of Illinois Chicago4 papers (2013–2021)Behrang Mahjani · Norwegian Institute of Public Health3 papers (2020–2021)